Pathogenic variants in DNM1 have been reported in association with early‐onset epileptic encephalopathy (including West and Lennox‐Gastaut syndromes), intractable seizures starting within the first year of life, motor impairments, and severe to profound ID (Allen et al., 2016; Deng et al., 2016; Epi4K Consortium; Epilepsy Phenome/Genome Project, 2013; Euro E‐RESC, EpilepsyPhenome/Genome P, Epi4K Constorium, 2014; Nakashima et al., 2016) (Table 1). This evidence concerns the gene DNM1 and epilepsy.